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Mechanistic Deep Dive
Prion Protein
- Normal: PrPC (cellular)
- Misfolded: PrPSc (scrapie-like)
- α-helix â β-sheet
- Self-propagating
- Resistant to proteases (in part)
RT-QuIC Mechanism
- Real-time quaking-induced conversion
- Recombinant PrP added to CSF
- Misfolded PrP seeds aggregation
- Detected by fluorescence
- Very sensitive + specific
CSF 14-3-3
- Marker of neuronal damage
- Less specific than RT-QuIC
- Can be elevated in other rapidly progressive encephalopathies
Recent Updates
sCJD Subtypes
- MM1, MM2, MV1, MV2, VV1, VV2 based on PRNP codon 129 + PrPSc type
- Different presentations
Anti-Prion Therapies
- PRN100 (monoclonal antibody) trials
- BIIB104 (antisense oligonucleotide)
- Limited efficacy so far
Plasma Biomarkers
- NfL emerging marker
- Plasma α-syn
High-Yield Specialist Points
Heidenhain Variant CJD
- Visual symptoms predominant initially
- Occipital lobe involvement
- Cortical blindness can result
Brownell-Oppenheimer Variant
- Cerebellar predominant
- Ataxia early
Variant CJD Pulvinar Sign
- Bilateral pulvinar (posterior thalamic) hyperintensity
- FLAIR/DWI
- Specific to vCJD
Familial Prion Mutations
- E200K, V210I (CJD)
- D178N (FFI with codon 129 M; CJD with V)
- P102L (GSS)
Fatal Familial Insomnia (FFI)
- D178N + 129M
- Insomnia â autonomic dysfunction â motor â death
- Thalamus prominent
- Severe REM disturbance
Gerstmann-StrÀussler-Scheinker
- Cerebellar ataxia primary
- Late cognitive
- Longer course
- P102L common
Autoimmune Encephalitis Mimics CJD
- Rapidly progressive
- Treatable (immunotherapy)
- Always rule out before declaring CJD
- Especially anti-LGI1, anti-NMDA-R, others
Limbic Encephalitis
- Mesial temporal involvement on MRI
- Seizures, amnesia
- Autoimmune or paraneoplastic
- Treatable
Sneddon Syndrome
- Livedo reticularis + recurrent strokes
- APS often
- Cognitive decline
Anti-IgLON5 Syndrome
- REM + non-REM sleep disorder
- Bulbar
- Movement
- Chorea, parkinsonism
- Hyperphosphorylated tau on autopsy
- Immunotherapy partial response
NORSE (New-Onset Refractory Status Epilepticus)
- Often autoimmune
- Refractory seizures
- Immunotherapy
- See Ch372
Hashimoto Encephalopathy
- SREAT (steroid-responsive encephalopathy associated with autoimmune thyroiditis)
- Anti-TPO antibodies high
- Subacute
- Steroid-responsive
- Mimics CJD
- Always check anti-TPO in rapidly progressive
Adult-Onset Leukodystrophies
- Adult metachromatic
- ALD (X-linked)
- Vanishing white matter
- Pelizaeus-Merzbacher-like
- Genetic testing
Cerebrotendinous Xanthomatosis
- CYP27A1
- Cataracts + tendon xanthomas + neurological
- Chenodeoxycholic acid
Pearls
- Prion (sCJD): rapid + myoclonus + ataxia + visual
- MRI cortical ribboning, BG hyperintensity
- RT-QuIC best CSF test
- vCJD: BSE, younger, psychiatric, pulvinar sign
- No treatment for prion
- Hashimoto encephalopathy mimics CJD â steroid-responsive
- Autoimmune encephalitis treatable
- VITAMINS mnemonic for rapidly progressive dementia
- Whipple CNS: oculomasticatory myorhythmia
- Wilson always consider young
- Reversible/treatable causes â rule out before declaring degenerative!