385.1 ð é«åžçç
385.1.1 Pathophysiology
- Prion protein (PrPC normal cellular) misfolds to PrPSc (scrapie)
- Templates further misfolding (self-propagating)
- Aggregates â neuronal death
- Resistant to standard sterilization
385.1.2 Classification
Sporadic (~ 85%): - Sporadic CJD (sCJD) â most common - Variably protease-sensitive prionopathy
Genetic (~ 15%): - Familial CJD (fCJD) â PRNP mutations - Gerstmann-StrÀussler-Scheinker (GSS) â ataxia + late dementia - Fatal familial insomnia (FFI) â insomnia, autonomic, motor
Acquired (rare): - Variant CJD (vCJD) â bovine spongiform encephalopathy (BSE, âmad cowâ) - Iatrogenic CJD â dural grafts, growth hormone (historical), neurosurgery instruments - Kuru â historic, Papua New Guinea (ritualistic cannibalism)
385.1.3 Sporadic CJD Features
- Mean onset 65 (range 40-90)
- Rapid progression (median survival 4-7 months from onset)
- Rapidly progressive dementia
- Myoclonus (startle myoclonus characteristic)
- Cerebellar signs (ataxia)
- Visual changes (Heidenhain variant)
- Behavioral changes
- Pyramidal + extrapyramidal signs
- Akinetic mutism (terminal)
385.1.4 Variant CJD (vCJD)
- BSE-related
- Younger (mean 28)
- Longer course (~ 14 months)
- Psychiatric symptoms early
- Painful dysesthesia
- Pulvinar sign on MRI (bilateral thalamic)
- Tonsillar biopsy can detect PrPSc
385.1.5 Diagnosis
MRI (very useful): - Cortical ribboning on DWI (cortex bright) - Basal ganglia hyperintensity on DWI/FLAIR - Distribution variable
EEG: - Periodic sharp wave complexes (PSWCs) in sCJD (late, ~ 65% sensitive) - Other patterns variable
CSF: - RT-QuIC (real-time quaking-induced conversion) â most accurate, > 95% sensitivity + specificity - 14-3-3 protein â sensitive but less specific - Total tau â â supportive - Normal cells + glucose + mild protein
Brain biopsy/autopsy: - Spongiform vacuolation - PrPSc immunostaining - Gold standard
385.1.6 Treatment
- No effective treatment
- Supportive
- Anti-prion drugs (quinacrine, doxycycline) tried â unsuccessful
- Investigational antisense (PRN100, BIIB104)
385.1.7 Classification (Frascati Criteria 2007)
- Asymptomatic neurocognitive impairment (ANI)
- Mild neurocognitive disorder (MND)
- HIV-associated dementia (HAD) â severe
385.1.9 Features
- Subcortical pattern: psychomotor slowing, attention, executive
- Motor: bradykinesia, gait
- Behavioral: apathy, depression
385.1.10 Treatment
- cART (some agents better CNS penetration â CHARTER score)
- Supportive
385.1.10.0.1 Neurosyphilis
- Tabes dorsalis
- General paresis
- Meningovascular
- Asymptomatic on LP
- Tests: VDRL CSF, treponemal serum
- Treatment: IV penicillin G 18-24 million units/day à 10-14 days
385.1.10.0.2 Whipple Disease (CNS)
- Tropheryma whipplei
- Oculomasticatory myorhythmia (pathognomonic!)
- Dementia, ataxia, ophthalmoplegia
- Often GI symptoms
- PCR or biopsy
- Treatment: ceftriaxone + TMP-SMX or doxycycline + hydroxychloroquine
385.1.10.0.3 Autoimmune Encephalitis
- See Ch389 (Neuroimmunology)
- Subacute cognitive decline + psychiatric + seizures
- Antibody-mediated:
- Anti-NMDA-R (young women, paraneoplastic ovarian teratoma; psychiatric â seizures â movement â autonomic)
- Anti-LGI1 (faciobrachial dystonic seizures + amnesia + hyponatremia)
- Anti-CASPR2
- Anti-GAD65
- Treatment: immunotherapy
385.1.10.0.4 Paraneoplastic Limbic Encephalitis
- Onconeural antibodies (Hu, Ma2, CV2, others)
- Underlying cancer (SCLC, testicular, breast, ovarian)
- Treat cancer + immunotherapy
385.1.10.0.5 Toxic / Metabolic / Nutritional
- B12 deficiency â subacute combined degeneration + cognitive
- Wernicke-Korsakoff â thiamine
- Heavy metals â lead, mercury, arsenic
- Hepatic encephalopathy
- Uremic encephalopathy
- Hypothyroidism (myxedema dementia)
- Hyperparathyroidism
- Hashimoto encephalopathy (steroid-responsive)
- CO poisoning
- Alcohol-related dementia
- Substance-induced
385.1.10.0.6 Leukodystrophies (Adult-Onset)
- Adult-onset metachromatic leukodystrophy
- Adrenoleukodystrophy (X-linked)
- Cerebrotendinous xanthomatosis
- CADASIL (see Ch383)
385.1.10.0.7 Mitochondrial Diseases
- MELAS, MERRF
- Maternal inheritance
- Multisystem (lactic acidosis, stroke-like episodes)
- mtDNA testing
385.1.10.0.8 Neurometabolic
- Wilson disease (always test in young < 40 with movement + cognitive)
- Niemann-Pick C
- Storage diseases
- Various
385.1.10.0.9 Approach to Rapidly Progressive Dementia
- Workup more extensive
- Consider CJD, autoimmune, infectious, metabolic, paraneoplastic, vascular (multi-infarct), neoplastic, toxic, structural
- LP, MRI, EEG, autoimmune/paraneoplastic panels, B12, thyroid, syphilis, HIV
- Treatable etiologies first!
385.1.10.1 𩺠åºé鿥
- Prion (sCJD): rapid dementia + myoclonus + ataxia + visual + behavioral
- CJD diagnosis: MRI (cortical ribbon, BG bright) + RT-QuIC + 14-3-3
- No treatment for prion
- vCJD: BSE, younger, psychiatric, pulvinar sign
- HAND: subcortical, on cART
- Neurosyphilis: VDRL CSF, IV penicillin
- Whipple CNS: oculomasticatory myorhythmia pathognomonic
- Autoimmune encephalitis: anti-NMDA-R, anti-LGI1 â immunotherapy
- Treatable causes of dementia must rule out